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Cited by 6Dental Implant Techniques and OutcomesDental materials and restorationsdental development and anomalies

Prosthetic rehabilitation of a patient with X-linked hypophosphatemia using dental implants: a case report and review of the literature

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James, Martin, Roudsari, Reza Vahid·2019·International Journal of Implant Dentistry
DOI 10.1186/s40729-019-0169-3PMC PMC6475631
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Abstract

BACKGROUND: X-linked hypophosphatemia is associated with a range of dental problems, many of which may result in early loss of the dentition. Most patients, but especially young adults, are likely to desire fixed prosthodontic replacements, and dental implants may be the preferred solution in many cases. The use of dental implants to rehabilitate this patient group has not been widely studied with the literature limited to a small number of case reports with limited follow-up. CASE PRESENTATION: This case report describes the dental journey of a young adult with X-linked hypophosphatemia, his eventual tooth loss and rehabilitation with multiple dental implants. Over 10 years' follow-up of three of the fixtures is presented. CONCLUSIONS: This case report shows a common presentation and progression of a patient with X-linked hypophosphatemia and will hopefully provide further positive evidence for the clinician to rely on when considering dental implant based treatments for such patients.

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  • The spectrum of long-term follow-up in included reports ranges from reporting on the achievement of dental treatment without further monitoring to less frequent reports with more than a decade of monitoring.

    “The spectrum ranges from reporting on the achievement of dental treatment without further monitoring to less frequent reports with more than a decade of monitoring (e.g., Bergendal et al. 2015; Fernandes et al. 2016; James and Roudsari 2019).”

    From Dental Management of Genetic Dental Disorders: A Critical Review (2025) · cites this paper as James and Roudsari 2019

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Authors
James, M., & Roudsari, R. V.
Affiliations
  • University Dental Hospital of Manchester (GB)
  • University of Manchester (GB)
Corresponding author
James, Martin
ORCID
Venue
International Journal of Implant Dentistry
Publisher
Springer Science and Business Media LLC
Published
2019-04-22
Volume
5
Issue
1
Pages
15-15
ISSN
2198-4034 (ISSN-L)
DOI
10.1186/s40729-019-0169-3
PMC
PMC6475631
OpenAlex
W2942458471
Cited by
6
References
44
Citations by year
2025: 3 · 2021: 2 · 2020: 1
FWCI
0.84
Type
journal article
Language
en
Open access
Licence
Locations
  • International Journal of Implant Dentistry (publishedVersion, cc-by)
  • PubMed Central (publishedVersion, cc-by)
  • PubMed (publishedVersion)
  • Research Explorer (The University of Manchester) (publishedVersion)
  • DOAJ (DOAJ: Directory of Open Access Journals) (submittedVersion)
Topics
  • Health Sciences › Dentistry › Oral Surgery › Dental Implant Techniques and Outcomes
  • Health Sciences › Dentistry › Orthodontics › Dental materials and restorations
  • Life Sciences › Biochemistry, Genetics and Molecular Biology › Molecular Biology › dental development and anomalies
Keywords
X-linked hypophosphatemia, dental implants, prosthodontic rehabilitation, tooth loss, young adults, implant survival, long-term follow-up

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