Genetic fate mapping demonstrates contribution of epicardium-derived cells to the annulus fibrosis of the mammalian heart
Open accessAbstract
The annulus fibrosis electrically insulates the atria and ventricles, allowing the timed sequential beating of these structures that is necessary for efficient heart function. Abnormal development of the annulus fibrosis leads to persistence of accessory electrical pathways from atria to ventricles, providing the anatomical substrate for re-entrant cardiac arrhythmias such as Wolff-Parkinson-White syndrome. To better understand the development of the annulus fibrosis and the etiology of these cardiac arrhythmias, we used Cre-LoxP technology to assess the contribution of epicardium derived cells (EPDCs) to the annulus fibrosis. We found that EPDCs migrated into the region of the forming annulus fibrosis, marked by the protein periostin. These EPDCs also stained positive for procollagen I, suggesting that the EPDCs themselves synthesize proteins of the annulus fibrosis. To further test the hypothesis that EPDCs contribute to cells that synthesize the annulus fibrosis, we purified genetically marked EPDCs from the atrioventricular region and measured gene expression by quantitative PCR. These EPDCs were highly enriched for mRNAs encoding periostin, procollagen I, fibronectin I, vimentin, discoidin domain receptor 2, and tenascin C, markers of fibroblasts and components of the annulus fibrosis. In addition, these EPDCs were highly enriched for Snail, Smad1, Slug, and Twist1, markers for epithelial-to-mesenchymal transition (EMT), and a metalloprotease, Mmp2, that contributes to cellular migration. Our work provides for the first time definitive evidence that epicardium contributes to formation of the mammalian annulus fibrosis through EMT. Abnormalities of this differentiation process may underlie development of some forms of re-entrant atrioventricular tachycardia.
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AV mesenchymal cells are also generated from the epicardium via EpiMT starting around E12.5.
“AV mesenchymal cells are also generated from the epicardium via the epicardial-to-mesenchymal transition (EpiMT) starting around E12.5 (Fig. 1a).”
From Cell diversity and plasticity during atrioventricular heart valve EMTs (2023) · cites this paper as [23]
The Results report epicardium-derived cells at the atrioventricular junction with mesenchymal markers and evidence of epicardial-to-mesenchymal transition. The cited paper does not establish that this process starts around E12.5; its reported observations here are at E14.5 and later (page numbers unavailable in our copy). (LLM, conf=0.86)
Experimental — accuracy not yet measuredVia EpiMT, epicardial cells contribute to smooth muscle cells, vasculature, pericytes, and fibroblasts, including those of the AVC and annulus fibrosus.
“Via EpiMT, epicardial cells contribute to smooth muscle cells, vasculature, pericytes, and fibroblasts, including those of the atrioventricular canal (AVC) and the annulus fibrosus5,6,23,24.”
From Cell diversity and plasticity during atrioventricular heart valve EMTs (2023) · cites this paper as [23]
The Introduction describes epicardial cells undergoing EMT and their descendants differentiating into smooth muscle, endothelial, and fibroblast lineages. The Results show epicardium-derived cells becoming fibroblasts at the atrioventricular junction and contributing to the annulus fibrosus. The copy does not identify pericytes as a lineage to which they contribute. Page numbers are unavailable in the indexed passages. (LLM, conf=0.85)
Experimental — accuracy not yet measured
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“These cells gain migratory and invasive characteristics, trans-differentiate to mesenchyme, and populate the right and left lateral cardiac cushions, along with the annulus fi brosis 5,6,23,59 .”
Background
- Authors
- Zhou, B., von Gise, A., Ma, Q., Hu, Y. W., & Pu, W. T.
- Affiliations
- Boston Children's Hospital (US)
- Corresponding author
- Zhou, Bin
- Pu, William T.
- Venue
- Developmental Biology
- Publisher
- Elsevier BV
- Published
- 2010-02
- Volume
- 338
- Issue
- 2
- Pages
- 251-261
- ISSN
- 0012-1606 (ISSN-L)
- PMC
- PMC2815244
- OpenAlex
- W2024971066
- Cited by
- 163
- References
- 0
- Citations by year
- 2026: 4 · 2025: 3 · 2024: 8 · 2023: 6 · 2022: 5 · 2021: 6 · 2020: 12 · 2019: 10 · 2018: 15 · 2017: 8 · 2016: 13 · 2015: 12 · 2014: 10 · 2013: 13 · 2012: 17
- FWCI
- 5.11
- Type
- journal article
- Language
- en
- Open access
- bronze
- doi.org
- Licence
- www.elsevier.com/tdm/userlicense/1.0/ (tdm)
- www.elsevier.com/legal/tdmrep-license (tdm)
- www.elsevier.com/open-access/userlicense/1.0/ (vor, 1298 d)
- doi.org/10.15223/policy-017 (stm-asf)
- doi.org/10.15223/policy-037 (stm-asf)
- doi.org/10.15223/policy-012 (stm-asf)
- doi.org/10.15223/policy-029 (stm-asf)
- doi.org/10.15223/policy-004 (stm-asf)
- Locations
- Developmental Biology (publishedVersion)
- PubMed (publishedVersion)
- PubMed Central (acceptedVersion)
- Funders
- NIH (1R01HL094683)
- Topics
- Life Sciences › Biochemistry, Genetics and Molecular Biology › Molecular Biology › Congenital heart defects research
- Health Sciences › Medicine › Cardiology and Cardiovascular Medicine › Cardiac electrophysiology and arrhythmias
- Health Sciences › Medicine › Cardiology and Cardiovascular Medicine › Cardiac Fibrosis and Remodeling
- Keywords
- epicardium, epicardial-derived cells, atrioventricular junction, periostin, epithelial-mesenchymal transition, cardiac fibroblasts, type I procollagen, cardiac arrhythmias, Wolff-Parkinson-White syndrome, atrioventricular reentrant tachycardia, heart development, cell migration, MMP-2
- MeSH terms
- Animals, Arrhythmias, Cardiac, Cell Movement, Fibrosis, Heart Atria, Heart Conduction System, Heart Ventricles, Myocardium, Pericardium, RNA, Messenger, Gene Expression Profiling, Mice, Cardiac Electrophysiology
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