Cited by 114Alzheimer's disease research and treatmentsNeurobiology and Insect Physiology ResearchAmyotrophic Lateral Sclerosis Research

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Functional genomic screen and network analysis reveal novel modifiers of tauopathy dissociated from tau phosphorylation

Open access
Ambegaokar, Surendra S., Jackson, George R.·2011·Human Molecular Genetics

Abstract

A functional genetic screen using loss-of-function and gain-of-function alleles was performed to identify modifiers of tau-induced neurotoxicity using the 2N/4R (full-length) isoform of wild-type human tau expressed in the fly retina. We previously reported eye pigment mutations, which create dysfunctional lysosomes, as potent modifiers; here, we report 37 additional genes identified from ∼1900 genes screened, including the kinases shaggy/GSK-3beta, par-1/MARK, CamKI and Mekk1. Tau acts synergistically with Mekk1 and p38 to down-regulate extracellular regulated kinase activity, with a corresponding decrease in AT8 immunoreactivity (pS202/T205), suggesting that tau can participate in signaling pathways to regulate its own kinases. Modifiers showed poor correlation with tau phosphorylation (using the AT8, 12E8 and AT270 epitopes); moreover, tested suppressors of wild-type tau were equally effective in suppressing toxicity of a phosphorylation-resistant S11A tau construct, demonstrating that changes in tau phosphorylation state are not required to suppress or enhance its toxicity. Genes related to autophagy, the cell cycle, RNA-associated proteins and chromatin-binding proteins constitute a large percentage of identified modifiers. Other functional categories identified include mitochondrial proteins, lipid trafficking, Golgi proteins, kinesins and dynein and the Hsp70/Hsp90-organizing protein (Hop). Network analysis uncovered several other genes highly associated with the functional modifiers, including genes related to the PI3K, Notch, BMP/TGF-β and Hedgehog pathways, and nuclear trafficking. Activity of GSK-3β is strongly upregulated due to TDP-43 expression, and reduced GSK-3β dosage is also a common suppressor of Aβ42 and TDP-43 toxicity. These findings suggest therapeutic targets other than mitigation of tau phosphorylation.

Overview

AI snapshot

Written from the paper’s full text.

TL;DR

Two Drosophila enhancer–suppressor screens identified 37 modifiers of wild-type human tau toxicity, with 40 total modifiers including previously reported pigment genes. The results dissociate tau toxicity from tau phosphorylation and implicate GSK-3β, ERK/p38 signaling, autophagy, RNA-associated processes, and other pathways as therapeutic targets.

Key findings

  • From ∼1900 lines screened, 37 genes were identified: 23 modifiers from the P lethal LOF screen (11 suppressors, 12 enhancers) and 14 from the EY screen; adding white, brown, and rosy gave 40 total modifiers.
  • Tau phosphorylation did not correlate with toxicity: 18 of 40 modifiers showed no significant AT8 difference, 22 of 40 showed significant changes but with no suppressor/enhancer pattern; suppressors of wild-type tau also suppressed the phosphorylation-resistant S11A isoform, while the non-toxic S2A isoform was resistant to all enhancers.
  • Tau synergized with Mekk1/p38 to reduce ERK activity: co-expression of tau and Mekk1 produced a profound reduction (∼60%) in phospho-ERK, while Mekk1 overexpression increased p38 activity and decreased AT8.
  • GSK-3β/shaggy was a common suppressor of tau, Aβ42, and TDP-43 toxicity; TDP-43Q331K strongly increased GSK-3β activity, indicated by reduced pGSK-3β[Ser9] (P = 0.004).

Methods

  • The gl-tau Drosophila eye model expressed wild-type full-length 2N/4R human tau; the P lethal collection provided LOF alleles (920 stocks screened) and the EY collection provided overexpression/insertion alleles (895 annotated stocks screened), with blinded phenotypic scoring and validation with additional alleles where possible.
  • Eye phenotypes were scored by roughness, necrosis, and eye volume using SEM, light microscopy, and 3D reconstructions; immunoblots measured total tau, phospho-tau (AT8, 12E8, AT270), phospho-p38, phospho-ERK, and phospho-GSK-3β[Ser9], with genetic tests against Q108, Aβ42, TDP-43Q331K, S11A, and S2A.
  • Computational network analysis used Endeavor-HighFly on 35 annotated modifiers, compiled genes with P < 0.05, applied inclusion criteria based on recurrence across hit networks, and visualized the network with Cytoscape; human orthologs were assigned using PANTHER.

Limitations

  • Stated in the paper: the screen was not saturating, covering less than 20% of the ∼12,000 fly genes; it was selective for dominant/haploinsufficiency effects and essential genes in the P lethal screen, and subtle modifiers may have been excluded by the robust-phenotype criterion.
  • Stated in the paper: the eye/retina may not be the ideal tissue to observe effects of some genes, and the computational network neither represents a full genomic network nor includes all demonstrated or putative modifiers.
  • Evident from the text: only 895 annotated EY stocks were screened, 17 of 40 modifier genes had only a single allele tested, and several modifiers were non-annotated; phosphorylation analysis was limited to selected epitopes, and many functional categories were not mechanistically resolved.

Model-written summary. Check it against the paper before relying on it.

Integrity signals

Registry

Crossref · 10.1093/hmg/ddr432

Cites

365 of 365 references verified0 citation errors · 0 not checkable

Statistics

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Figures

Figure 1. Genetic modifiers of tau-induced neurotoxicity identified from P lethal LOF screen. ‘Control’: w1118/+;gl-tau/+. All other panels, except wild-type, contain one copy of gl-tau transgene in trans to one disrupted copy of the gene listed in the panel. Genes are listed alphabetically; non-annotated genes comprise the bottom row. Arrows point to necrotic plaques that were initially identified by light microscopy.
Figure 1. Genetic modifiers of tau-induced neurotoxicity identified from P lethal LOF screen. ‘Control’: w1118/+;gl-tau/+. All other panels, except wild-type, contain one copy of gl-tau transgene in trans to one disrupted copy of the gene listed in the panel. Genes are listed alphabetically; non-annotated genes comprise the bottom row. Arrows point to necrotic plaques that were initially identified by light microscopy.CC BY-NC · PubMed Central
Figure 2. Modifiers of tau-induced neurotoxicity show little effect on apoptosis. The 37 modifiers identified from P lethal and EY functional screens were tested for their ability to suppress the effects of the proapoptotic gene hid. P lethal control: w1118;GMR-hid/+. All other P lethal genotypes have one copy of GMR-hid in trans to one disrupted copy of the listed gene. EY control: GMR-GAL4/w1118;GMR-hid/+. All other EY genotypes have one copy of GMR-GAL4 on the first chromosome and one copy of GMR-hid in trans to the affected listed gene. Genes are listed alphabetically. Nearly all modifiers failed to show an effect on apoptosis when compared with controls. CamKI and Hr39 showed a moderate suppression of apoptosis but enhanced tau toxicity. Modifiers oho23B, Tango5 and Tis11 showed mildly increased phenotypes when compared with hid.
Figure 2. Modifiers of tau-induced neurotoxicity show little effect on apoptosis. The 37 modifiers identified from P lethal and EY functional screens were tested for their ability to suppress the effects of the proapoptotic gene hid. P lethal control: w1118;GMR-hid/+. All other P lethal genotypes have one copy of GMR-hid in trans to one disrupted copy of the listed gene. EY control: GMR-GAL4/w1118;GMR-hid/+. All other EY genotypes have one copy of GMR-GAL4 on the first chromosome and one copy of GMR-hid in trans to the affected listed gene. Genes are listed alphabetically. Nearly all modifiers failed to show an effect on apoptosis when compared with controls. CamKI and Hr39 showed a moderate suppression of apoptosis but enhanced tau toxicity. Modifiers oho23B, Tango5 and Tis11 showed mildly increased phenotypes when compared with hid.CC BY-NC · PubMed Central
Figure 3. Genetic modifiers of tau-induced neurotoxicity identified from EY collection screen. ‘Control’: GMR-GAL4/+;gl-tau/+. All other panels contain one copy of GMR-GAL4 on the X chromosome and one copy of gl-tau transgene in trans to the gene listed in the panel affected by the EY element. Genes are listed alphabetically.
Figure 3. Genetic modifiers of tau-induced neurotoxicity identified from EY collection screen. ‘Control’: GMR-GAL4/+;gl-tau/+. All other panels contain one copy of GMR-GAL4 on the X chromosome and one copy of gl-tau transgene in trans to the gene listed in the panel affected by the EY element. Genes are listed alphabetically.CC BY-NC · PubMed Central
Figure 4. Quantification of eye volumes of modifiers. (A) Three-dimensional reconstructions of representative eyes of wild-type, control gl-tau (+/gl-tau), enhancer (Hop) and suppressor (shaggy) phenotypes. (B) Estimated eye volumes of modifier phenotypes from P lethal and EY screens indicated in scatter plots. Blue, suppressors; red, enhancers; black, control; green, wild-type. Black horizontal lines delineate range of control eye volumes; suppressors have larger eye volumes, whereas enhancers have smaller eye volumes when compared with control.
Figure 4. Quantification of eye volumes of modifiers. (A) Three-dimensional reconstructions of representative eyes of wild-type, control gl-tau (+/gl-tau), enhancer (Hop) and suppressor (shaggy) phenotypes. (B) Estimated eye volumes of modifier phenotypes from P lethal and EY screens indicated in scatter plots. Blue, suppressors; red, enhancers; black, control; green, wild-type. Black horizontal lines delineate range of control eye volumes; suppressors have larger eye volumes, whereas enhancers have smaller eye volumes when compared with control.CC BY-NC · PubMed Central
Figure 5. Computational tau toxicity modifier network can predict novel tau modifiers. (A) Computational predictions of tau interactors based on high association with hits from the functional genetic screen. Hits from the functional screen are marked with asterisks. Size of the nodes is proportional to degree of connectivity with other genes in the network. Although all genes selected for inclusion have high connectivity to many genes in the network (see Materials and Methods for parameters of inclusion), for clarity only the strongest interactions with a quantified interaction (P-value <0.001) are indicated in blue lines. Each functional group is coded with a unique color; a node was color-divided to indicate whether multiple functions are attributed to that gene. (B) Network association genes—mitochondrial gene, Tom34, and RNA trafficking gene, csul—both strongly modify tau toxicity, showing strong suppression when overexpressed (GOF) and enhanced toxicity when expression is reduced (LOF). Tom34 and csul expression do not modify apoptosis (as assayed using the GMR-GAL4;GMR-hid phenotype), nor show any intrinsic eye phenotypes (as assayed with GMR-GAL4 alone). However, both show effects on the GMR-GAL4::UAS-Q108 phenotype—Tom34 suppresses Q108 toxicity, whereas csul enhances toxicity.
Figure 5. Computational tau toxicity modifier network can predict novel tau modifiers. (A) Computational predictions of tau interactors based on high association with hits from the functional genetic screen. Hits from the functional screen are marked with asterisks. Size of the nodes is proportional to degree of connectivity with other genes in the network. Although all genes selected for inclusion have high connectivity to many genes in the network (see Materials and Methods for parameters of inclusion), for clarity only the strongest interactions with a quantified interaction (P-value <0.001) are indicated in blue lines. Each functional group is coded with a unique color; a node was color-divided to indicate whether multiple functions are attributed to that gene. (B) Network association genes—mitochondrial gene, Tom34, and RNA trafficking gene, csul—both strongly modify tau toxicity, showing strong suppression when overexpressed (GOF) and enhanced toxicity when expression is reduced (LOF). Tom34 and csul expression do not modify apoptosis (as assayed using the GMR-GAL4;GMR-hid phenotype), nor show any intrinsic eye phenotypes (as assayed with GMR-GAL4 alone). However, both show effects on the GMR-GAL4::UAS-Q108 phenotype—Tom34 suppresses Q108 toxicity, whereas csul enhances toxicity.CC BY-NC · PubMed Central
Figure 6. Modifying tau toxicity does not require altering tau phosphorylation state. (A) Immunoblots from tau toxicity modifiers probed for total tau (T46 or E178) and tau phosphorylation at S202/T205 (AT8). β-Tubulin or β-actin shown as loading control. P lethal control: w1118/+;gl-tau/+. EY control: GMR-GAL4/+;gl-tau/+. Genes labeled in red designate enhancers, whereas genes labeled in blue are suppressors. Blots for EY hits were visualized by two-color immunoblots with fluorescent secondaries and imaged with the Odyssey Near-IR Scanner (Li-Cor), but are shown in grayscale. Two-color immunoblots allowed for visualization and measurement of total tau (E178, rabbit IgG) and AT8 (mouse IgG) simultaneously. (B) Quantification of phosphorylated tau. Modifiers did not significantly alter total tau expression. AT8 levels were normalized to total tau; significant differences (P < 0.05) when compared with control are marked with asterisks. Approximately half (18 of 40) of the modifiers showed no significant differences in phospho-tau when compared with control. The other half (22 of 40) showed a significant difference in AT8; however, no pattern of phosphorylation correlated with enhancement or suppression of the tau phenotype. (C) Scatterplot of the mean values for AT8 signal of the 40 modifiers identified shows little difference in phosphorylation state between enhancers and suppressors.
Figure 6. Modifying tau toxicity does not require altering tau phosphorylation state. (A) Immunoblots from tau toxicity modifiers probed for total tau (T46 or E178) and tau phosphorylation at S202/T205 (AT8). β-Tubulin or β-actin shown as loading control. P lethal control: w1118/+;gl-tau/+. EY control: GMR-GAL4/+;gl-tau/+. Genes labeled in red designate enhancers, whereas genes labeled in blue are suppressors. Blots for EY hits were visualized by two-color immunoblots with fluorescent secondaries and imaged with the Odyssey Near-IR Scanner (Li-Cor), but are shown in grayscale. Two-color immunoblots allowed for visualization and measurement of total tau (E178, rabbit IgG) and AT8 (mouse IgG) simultaneously. (B) Quantification of phosphorylated tau. Modifiers did not significantly alter total tau expression. AT8 levels were normalized to total tau; significant differences (P < 0.05) when compared with control are marked with asterisks. Approximately half (18 of 40) of the modifiers showed no significant differences in phospho-tau when compared with control. The other half (22 of 40) showed a significant difference in AT8; however, no pattern of phosphorylation correlated with enhancement or suppression of the tau phenotype. (C) Scatterplot of the mean values for AT8 signal of the 40 modifiers identified shows little difference in phosphorylation state between enhancers and suppressors.CC BY-NC · PubMed Central
Figure 7. p38 interacts synergistically with tau to regulate ERK activity and ksr decreases GSK-3β and ERK activities. (A) Immunoblots and (B) quantification of kinase activity induced by Mekk1 overexpression, which enhanced tau toxicity. Mekk1 overexpression induced a modest significant increase in p38 activity (phospho-p38) independent of human tau expression. ERK activity (phospho-ERK) was equivalent for tau expression alone (first lane) and Mekk1 expression alone (third lane); however, tau and Mekk1 co-overexpression strongly reduced phospho-ERK levels (second lane). Overexpression of Mekk1 also strongly reduced S202/T205 tau phosphorylation levels (AT8), but did not alter total tau levels (T46). No significant difference was observed for GSK-3β activity (phospho-GSK-3β-Ser9). (C) Both enhancer bancal and suppressor ksr decrease ERK activity, but ksr also strongly reduced GSK-3β activity, while bancal trended to increase GSK-3β activity.
Figure 7. p38 interacts synergistically with tau to regulate ERK activity and ksr decreases GSK-3β and ERK activities. (A) Immunoblots and (B) quantification of kinase activity induced by Mekk1 overexpression, which enhanced tau toxicity. Mekk1 overexpression induced a modest significant increase in p38 activity (phospho-p38) independent of human tau expression. ERK activity (phospho-ERK) was equivalent for tau expression alone (first lane) and Mekk1 expression alone (third lane); however, tau and Mekk1 co-overexpression strongly reduced phospho-ERK levels (second lane). Overexpression of Mekk1 also strongly reduced S202/T205 tau phosphorylation levels (AT8), but did not alter total tau levels (T46). No significant difference was observed for GSK-3β activity (phospho-GSK-3β-Ser9). (C) Both enhancer bancal and suppressor ksr decrease ERK activity, but ksr also strongly reduced GSK-3β activity, while bancal trended to increase GSK-3β activity.CC BY-NC · PubMed Central
Figure 8. GSK-3β/shaggy is a common suppressor of S11A, Aβ42 and TDP-43 toxicity, whereas S2A is resistant to all enhancers. (A) Expression of the phosphorylation-resistant TauS11A isoform shows strong toxicity, stronger than TauWT expression. However, select suppressors of gl-TauWT were also able to suppress S11A toxicity. (B) Expression of the phosphorylation-resistant TauS2A isoforms shows no toxicity. All enhancers identified in the screen were tested against S2A phenotype; five representative enhancers are depicted. No enhancer could induce a rough eye phenotype with TauS2A. Western blots confirm robust expression of TauS2A protein with all enhancers assayed. (C) NC2α and SdhB, which suppressed both tau and polyglutamine toxicity, were tested for their effects on Aβ42 and TDP-43Q331K toxicity. Neither gene showed any significant effect on the GMR-GAL4::UAS-Aβ42 phenotype, nor on the GMR-GAL4::UAS-hTDP-43Q331K phenotype when compared with controls. However, shaggy/GSK-3β showed suppression of toxicity, as indicated by increased size and eye volume of the Aβ42 eye, and by increased color and pigment retention in the TDP-43 eye. Modifier ksr shows a mild suppression of Aβ42 and TDP-43 toxicity, although not as robust as sgg suppression. Scale bar, 100 μm. (D) Expression of hTDP-43Q331K shows a robust increase in GSK-3β activity, as indicated by western blot of reduced Ser9 phosphorylation of GSK-3β (P = 0.004).
Figure 8. GSK-3β/shaggy is a common suppressor of S11A, Aβ42 and TDP-43 toxicity, whereas S2A is resistant to all enhancers. (A) Expression of the phosphorylation-resistant TauS11A isoform shows strong toxicity, stronger than TauWT expression. However, select suppressors of gl-TauWT were also able to suppress S11A toxicity. (B) Expression of the phosphorylation-resistant TauS2A isoforms shows no toxicity. All enhancers identified in the screen were tested against S2A phenotype; five representative enhancers are depicted. No enhancer could induce a rough eye phenotype with TauS2A. Western blots confirm robust expression of TauS2A protein with all enhancers assayed. (C) NC2α and SdhB, which suppressed both tau and polyglutamine toxicity, were tested for their effects on Aβ42 and TDP-43Q331K toxicity. Neither gene showed any significant effect on the GMR-GAL4::UAS-Aβ42 phenotype, nor on the GMR-GAL4::UAS-hTDP-43Q331K phenotype when compared with controls. However, shaggy/GSK-3β showed suppression of toxicity, as indicated by increased size and eye volume of the Aβ42 eye, and by increased color and pigment retention in the TDP-43 eye. Modifier ksr shows a mild suppression of Aβ42 and TDP-43 toxicity, although not as robust as sgg suppression. Scale bar, 100 μm. (D) Expression of hTDP-43Q331K shows a robust increase in GSK-3β activity, as indicated by western blot of reduced Ser9 phosphorylation of GSK-3β (P = 0.004).CC BY-NC · PubMed Central
Figure 9. Modifiers of tau-induced neurotoxicity do not modify polyglutamine toxicity. The 37 modifiers identified from P lethal and EY screens were crossed to w1118;GMR-GAL4, UAS-Q108/CyO. Controls: w1118;GMR-GAL4, UAS-Q108/+. All other genotypes have one copy of GMR-GAL4, UAS-Q108. The gene listed refers to the allele affected by P element or EY element; genes are listed alphabetically. Most tau modifiers showed no effect on polyglutamine toxicity; only NC2α and SdhB showed suppression.
Figure 9. Modifiers of tau-induced neurotoxicity do not modify polyglutamine toxicity. The 37 modifiers identified from P lethal and EY screens were crossed to w1118;GMR-GAL4, UAS-Q108/CyO. Controls: w1118;GMR-GAL4, UAS-Q108/+. All other genotypes have one copy of GMR-GAL4, UAS-Q108. The gene listed refers to the allele affected by P element or EY element; genes are listed alphabetically. Most tau modifiers showed no effect on polyglutamine toxicity; only NC2α and SdhB showed suppression.CC BY-NC · PubMed Central

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Claims the paper makes

116 Own result · 79 Own interpretation · 26 Partly supported · 20 Supported · 18 No full text of the sources · 12 No basis given · 11 Own method · 7 Supported so far · 3 Couldn’t confirm · 2 Not supported · 2 Not checked yet · 1 Mixed support · accuracy not yet measured

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Show all 179 claims

  • Probably not a substantial claim. 50
  • It may state two separate claims as one. 85
  • The quote only partly states this claim. 1
118 of 118
  • The paper relies on this without support.

    Essential genes in Drosophila are more likely to have a homolog in vertebrates and thus may correspond to relevant human modifier genes in tauopathies.

    “Also, essential genes in the fly are more likely to have a homolog in vertebrates and thus may correspond to relevant human modifier genes in tauopathies.”
  • The paper relies on this without support.

    The UAS insertion can block transcription of the downstream gene if it is inserted in the opposite orientation.

    “however, the UAS insertion can also block transcription of the downstream gene if it is inserted in the opposite orientation.”
  • The paper relies on this without support.

    No LOF screen with a tauopathic animal model has previously been reported.

    “The P lethal collection represents solely LOF alleles, and no LOF screen with a tauopathic animal model has previously been reported.”
  • The paper relies on this without support.

    The large black plaques observed in gl-tau/Atg6 progeny indicate enhanced tau-induced toxicity.

    “Atg6 was included as an enhancer due to large black plaques in the anterior region of the eye that were commonly found in gl-tau/Atg6 progeny (see arrows in Fig. 1) that were not present in controls.”
  • The paper relies on this without support.

    Most tauopathies are idiopathic and lack causative mutations in MAPT.

    “However, most tauopathies are idiopathic and lack causative mutations in MAPT”
  • The paper relies on this without support.

    PHFs are primarily composed of hyperphosphorylated tau.

    “PHFs are primarily composed of ‘hyperphosphorylated’ tau; thus, increased tau phosphorylation is regarded as a key component in tau-related pathogenesis.”
  • The paper relies on this without support.

    Increased tau phosphorylation is a key component in tau-related pathogenesis.

    “PHFs are primarily composed of ‘hyperphosphorylated’ tau; thus, increased tau phosphorylation is regarded as a key component in tau-related pathogenesis.”
  • The paper relies on this without support.

    The sites mutated in S11A are commonly hyperphosphorylated in tauopathic tissue and are known to be phosphorylated by GSK-3β and CDK-5.

    “The sites mutated are ones commonly observed as hyperphosphorylated in tauopathic tissue and are known to be phosphorylated by key kinases such as GSK-3β and CDK-5.”
  • The paper relies on this without support.

    TDP-43Q331K is an amyotrophic lateral sclerosis-causing mutation.

    “an amyotrophic lateral sclerosis-causing mutation in TAR DNA Binding Protein-43, TDP-43Q331K”
  • The paper relies on this without support.

    sgg/GSK-3β and par-1/MARK-2 are known tau kinases.

    “of these, sgg/GSK-3β and par-1/MARK-2 are known tau kinases, validating the design of the screen to identify modifiers of tau or tau toxicity.”
  • The paper relies on this without support.

    The GMR-GAL4/y1w67c23;gl-tau/+ genotype has a suppressed phenotype compared to GMR-GAL4/+;gl-tau/+.

    “GMR-GAL4/y1w67c23;gl-tau/+ has a suppressed phenotype versus GMR-GAL4/+;gl-tau/+ (not shown)”
11 of 11

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Metadata

Authors
Ambegaokar, S. S., & Jackson, G. R.
Affiliations
The University of Texas Medical Branch at Galveston (US)
Corresponding author
Jackson, George R.
Venue
Human Molecular Genetics
Published
2011-09-23
Volume
20
Issue
24
Pages
4947-4977
ISSN
  • 0964-6906 (ISSN-L)
  • 1460-2083
OpenAlex
W2106473141
Cited by
113
References
367
Citations by year
2026: 5 · 2025: 4 · 2024: 5 · 2023: 6 · 2022: 8 · 2021: 11 · 2020: 6 · 2019: 10 · 2018: 6 · 2017: 8 · 2016: 8 · 2015: 10 · 2014: 10 · 2013: 8 · 2012: 8
FWCI
5.01
Type
journal article
Language
en
Open access
Licence
other-oa
Locations
  • Human Molecular Genetics (publishedVersion, other-oa)
  • PubMed (publishedVersion)
  • Europe PMC (PubMed Central) (submittedVersion, cc-by-nc)
  • PubMed Central (submittedVersion, cc-by-nc)
Funders
  • American Health Assistance Foundation
  • National Institutes of Health (5t32ns007449-15, 5p50ag016570-15)
  • University of California, Irvine
  • Mitchell Center for Neurodegenerative Diseases, University of Texas Medical Branch
  • National Institute on Aging (AG 16570)
  • National Institute of Mental Health (T32MH073526)
  • National Institute of Neurological Disorders and Stroke (NS040648, R01 NS046489, T32-NS07449)
  • National Institute of Environmental Health Sciences (P01ES016732, ES016732)
Topics
  • Life Sciences › Neuroscience › Cellular and Molecular Neuroscience › Alzheimer's disease research and treatments
  • Life Sciences › Neuroscience › Cellular and Molecular Neuroscience › Neurobiology and Insect Physiology Research
  • Health Sciences › Medicine › Clinical Neurology › Amyotrophic Lateral Sclerosis Research
Keywords
tauopathy, genetic modifiers, tau phosphorylation, ERK signaling, autophagy, TDP-43, amyloid-beta, Drosophila retina, network analysis, therapeutic target
MeSH terms
Glycogen Synthase Kinase 3 beta, Animals, DNA-Binding Proteins, Drosophila melanogaster, Enzyme Activation, Eye, Genetic Testing, Humans, Neurotoxins, Peptides, Phosphorylation, Genes, Suppressor, Amyloid beta-Peptides, tau Proteins, Computational Biology, Genomics, Tauopathies, Glycogen Synthase Kinase 3, Extracellular Signal-Regulated MAP Kinases, p38 Mitogen-Activated Protein Kinases, MAP Kinase Kinase Kinase 1, Mutant Proteins, Gene Regulatory Networks, Genes, Modifier

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